Overview

PHOspholamban RElated CArdiomyopathy STudy - Intervention

Status:
Completed
Trial end date:
2021-10-01
Target enrollment:
Participant gender:
Summary
Phospholamban (PLN) R14del mutation carriers may develop dilated cardiomyopathy (DCM) and/or arrhythmmogenic cardiomyopathy (ACM). Analogous to other inherited cardiomyopathies, the natural course of the disease is age-related ("age-related penetrance"); after a presymptomatic phase of variable length many PLN R14del-carriers progress to overt disease, and are diagnosed with either DCM or ARVC. PLN is a regulator of the sarcoplasmic reticulum Ca2+-ATPase (SERCA2a) pump in cardiac muscle and thereby important for maintaining Ca2+ homeostasis. Cardiac fibrosis appears to be an early manifestation of disease. The investigators hypothesize that treatment of presymptomatic PLN R14del-carriers with eplerenone, which by virtue of its mineralocorticoid(aldosterone)-blocking properties is a strong antifibrotic agent, reduces disease progression and postpones onset of overt disease.
Phase:
Phase 3
Details
Lead Sponsor:
M.p. van den Berg, MD, PhD, professor in Cardiology
Collaborators:
Netherlands: CVON, CardioVascular Research Netherlands
Netherlands: TCC, Trial Coordination Center UMCG
The Interuniversity Cardiology Institute of the Netherlands
University Medical Center Groningen
ZonMw: The Netherlands Organisation for Health Research and Development
Treatments:
Eplerenone
Spironolactone